U.S. flag

An official website of the United States government

Format

Send to:

Choose Destination

Classical Lissencephalies and Subcortical Band Heterotopias

MedGen UID:
408200
Concept ID:
C1955870
Disease or Syndrome
Synonyms: Agyria Pachygyria Band Spectrum; Agyria-Pachygyria-Band Spectrum; Band Heterotopia, Lissencephaly-Subcortical; Heterotopia, Lissencephaly-Subcortical Band; Heterotopias, Lissencephaly-Subcortical Band; Lissencephaly Subcortical Band Heterotopia; Lissencephaly-Subcortical Band Heterotopia; Lissencephaly-Subcortical Band Heterotopias

Definition

Disorders comprising a spectrum of brain malformations representing the paradigm of a diffuse neuronal migration disorder. They result in cognitive impairment; SEIZURES; and HYPOTONIA or spasticity. Mutations of two genes, LIS1, the gene for the non-catalytic subunit of PLATELET-ACTIVATING FACTOR ACETYLHYDROLASE IB; and DCX or XLIS, the gene for doublecortin, have been identified as the most common causes of disorders in this spectrum. Additional variants of classical (Type I) lissencephaly have been linked to RELN, the gene for reelin, and ARX, the gene for aristaless related homeobox protein. (From Leventer, R.J., et al, Mol Med Today. 2000 Jul;6(7):277-84 and Barkovich, A.J., et al, Neurology. 2005 Dec 27;65(12):1873-87.) [from MeSH]

Term Hierarchy

CClinical test,  RResearch test,  OOMIM,  GGeneReviews,  VClinVar  
  • CROGVClassical Lissencephalies and Subcortical Band Heterotopias

Professional guidelines

PubMed

Zhang YL, Jing XY, Zhen L, Pan M, Han J, Li DZ
Eur J Obstet Gynecol Reprod Biol 2022 Jul;274:28-32. Epub 2022 May 6 doi: 10.1016/j.ejogrb.2022.04.025. PMID: 35567955
Koenig M, Dobyns WB, Di Donato N
Eur J Paediatr Neurol 2021 Nov;35:147-152. Epub 2021 Oct 7 doi: 10.1016/j.ejpn.2021.09.013. PMID: 34731701
Shi X, Huang W, Lu J, He W, Liu Q, Wu J
Ann Hum Genet 2021 Mar;85(2):92-96. Epub 2020 Oct 7 doi: 10.1111/ahg.12407. PMID: 33026665

Recent clinical studies

Etiology

Chiba E, Sato N, Kimura Y, Shigemoto Y, Maki H, Arizono E, Hamamoto K, Taniguchi G, Iwasaki M, Ota M, Matsuda H, Nakagawa E
J Neuroimaging 2023 Sep-Oct;33(5):731-736. Epub 2023 Jun 25 doi: 10.1111/jon.13141. PMID: 37355835
Liang B, Yu D, Zhao W, Wang Y, Wu X, Chen L, Lin N, Huang H, Xu L
BMC Med Genomics 2022 Dec 21;15(1):268. doi: 10.1186/s12920-022-01423-5. PMID: 36544138Free PMC Article
Vriend I, Oegema R
Eur J Paediatr Neurol 2021 Nov;35:82-92. Epub 2021 Oct 9 doi: 10.1016/j.ejpn.2021.09.015. PMID: 34666232
Ito K, Nakata Y, Matsuda H, Sugai K, Watanabe M, Kamiya K, Kimura Y, Shigemoto Y, Okazaki M, Sasaki M, Sato N
Brain Dev 2014 Aug;36(7):578-84. Epub 2013 Aug 16 doi: 10.1016/j.braindev.2013.07.017. PMID: 23958594
Merwick A, O'Brien M, Delanty N
Epilepsia 2012 Sep;53 Suppl 4:81-91. doi: 10.1111/j.1528-1167.2012.03617.x. PMID: 22946725

Diagnosis

Chiba E, Sato N, Kimura Y, Shigemoto Y, Maki H, Arizono E, Hamamoto K, Taniguchi G, Iwasaki M, Ota M, Matsuda H, Nakagawa E
J Neuroimaging 2023 Sep-Oct;33(5):731-736. Epub 2023 Jun 25 doi: 10.1111/jon.13141. PMID: 37355835
Koenig M, Dobyns WB, Di Donato N
Eur J Paediatr Neurol 2021 Nov;35:147-152. Epub 2021 Oct 7 doi: 10.1016/j.ejpn.2021.09.013. PMID: 34731701
Vriend I, Oegema R
Eur J Paediatr Neurol 2021 Nov;35:82-92. Epub 2021 Oct 9 doi: 10.1016/j.ejpn.2021.09.015. PMID: 34666232
Adams DJ, Clark DA
Pediatr Clin North Am 2015 Apr;62(2):411-26. Epub 2015 Jan 22 doi: 10.1016/j.pcl.2014.11.005. PMID: 25836705
Merwick A, O'Brien M, Delanty N
Epilepsia 2012 Sep;53 Suppl 4:81-91. doi: 10.1111/j.1528-1167.2012.03617.x. PMID: 22946725

Therapy

Franco A, Pimentel J, Campos AR, Morgado C, Pinelo S, Ferreira AG, Bentes C
Epileptic Disord 2016 Dec 1;18(4):426-430. doi: 10.1684/epd.2016.0878. PMID: 27965181
Herbst SM, Proepper CR, Geis T, Borggraefe I, Hahn A, Debus O, Haeussler M, von Gersdorff G, Kurlemann G, Ensslen M, Beaud N, Budde J, Gilbert M, Heiming R, Morgner R, Philippi H, Ross S, Strobl-Wildemann G, Muelleder K, Vosschulte P, Morris-Rosendahl DJ, Schuierer G, Hehr U
Brain Dev 2016 Apr;38(4):399-406. Epub 2015 Oct 19 doi: 10.1016/j.braindev.2015.10.001. PMID: 26494205
Østergaard JR, Graakjær J, Brandt C, Birkebæk NH
Eur J Med Genet 2012 Jan;55(1):22-6. Epub 2011 Oct 24 doi: 10.1016/j.ejmg.2011.09.004. PMID: 22085993
Cukiert A, Mariani PP, Burattini JA, Cukiert CM, Forster C, Baise C, Argentoni-Baldochi M, Mello V
Epilepsia 2009 Dec;50(12):2667-9. Epub 2009 Aug 8 doi: 10.1111/j.1528-1167.2009.02255.x. PMID: 19674051
Koutsouraki E, Timplalexi G, Papadopoulou Z, Costa V, Baloyannis S
Int J Neurosci 2008 Mar;118(3):343-8. doi: 10.1080/00207450601050261. PMID: 18300007

Prognosis

Vriend I, Oegema R
Eur J Paediatr Neurol 2021 Nov;35:82-92. Epub 2021 Oct 9 doi: 10.1016/j.ejpn.2021.09.015. PMID: 34666232
Adams DJ, Clark DA
Pediatr Clin North Am 2015 Apr;62(2):411-26. Epub 2015 Jan 22 doi: 10.1016/j.pcl.2014.11.005. PMID: 25836705
Poduri A, Evrony GD, Cai X, Walsh CA
Science 2013 Jul 5;341(6141):1237758. doi: 10.1126/science.1237758. PMID: 23828942Free PMC Article
Mokánszki A, Körhegyi I, Szabó N, Bereg E, Gergev G, Balogh E, Bessenyei B, Sümegi A, Morris-Rosendahl DJ, Sztriha L, Oláh E
J Child Neurol 2012 Dec;27(12):1534-40. Epub 2012 Mar 8 doi: 10.1177/0883073811436326. PMID: 22408144
Dijkmans TF, van Hooijdonk LW, Fitzsimons CP, Vreugdenhil E
Cent Nerv Syst Agents Med Chem 2010 Mar;10(1):32-46. doi: 10.2174/187152410790780118. PMID: 20236041

Clinical prediction guides

Chiba E, Kimura Y, Shimizu-Motohashi Y, Miyagawa N, Ota M, Shigemoto Y, Ohnishi M, Nakaya M, Nakagawa E, Sasaki M, Sato N
Neuroradiology 2022 Apr;64(4):825-836. Epub 2021 Oct 25 doi: 10.1007/s00234-021-02836-2. PMID: 34693484
Di Donato N, Chiari S, Mirzaa GM, Aldinger K, Parrini E, Olds C, Barkovich AJ, Guerrini R, Dobyns WB
Am J Med Genet A 2017 Jun;173(6):1473-1488. Epub 2017 Apr 25 doi: 10.1002/ajmg.a.38245. PMID: 28440899Free PMC Article
Ito K, Nakata Y, Matsuda H, Sugai K, Watanabe M, Kamiya K, Kimura Y, Shigemoto Y, Okazaki M, Sasaki M, Sato N
Brain Dev 2014 Aug;36(7):578-84. Epub 2013 Aug 16 doi: 10.1016/j.braindev.2013.07.017. PMID: 23958594
Mokánszki A, Körhegyi I, Szabó N, Bereg E, Gergev G, Balogh E, Bessenyei B, Sümegi A, Morris-Rosendahl DJ, Sztriha L, Oláh E
J Child Neurol 2012 Dec;27(12):1534-40. Epub 2012 Mar 8 doi: 10.1177/0883073811436326. PMID: 22408144
Dijkmans TF, van Hooijdonk LW, Fitzsimons CP, Vreugdenhil E
Cent Nerv Syst Agents Med Chem 2010 Mar;10(1):32-46. doi: 10.2174/187152410790780118. PMID: 20236041

Recent systematic reviews

Kurzbuch AR, Cooper B, Israni A, Ellenbogen JR
Childs Nerv Syst 2023 Feb;39(2):451-462. Epub 2022 Aug 6 doi: 10.1007/s00381-022-05638-w. PMID: 35933521

Supplemental Content

Table of contents

    Practice guidelines

    • PubMed
      See practice and clinical guidelines in PubMed. The search results may include broader topics and may not capture all published guidelines. See the FAQ for details.

    Recent activity

    Your browsing activity is empty.

    Activity recording is turned off.

    Turn recording back on

    See more...